Making Every Subject Count: A Case Study of Drug Development Path for Medication in a Pediatric Rare Disease

نویسندگان

  • I Bhattacharya
  • Z Manukyan
  • P Chan
  • L Harnisch
  • A Heatherington
چکیده

Approximately 50% of rare diseases are evident in children. Fatal disease prognosis and lack of treatments causes 30% of affected children to not live past their fifth birthday. This clear sense of urgency demands innovation and acceleration in drug development. A case study is discussed highlighting the need for data-rich phase I study design, extensive use of modeling and simulation, use of diverse data sources, and input from collaborators to respond to this urgent call.

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عنوان ژورنال:

دوره 100  شماره 

صفحات  -

تاریخ انتشار 2016